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bioRxiv · 10.1101/2025.02.15.637872

Maternal age and genome-wide failure of meiotic recombination are associated with triploid conceptions in humans

Abstract

Triploid and haploid conceptions are not viable and are a common occurrence in humans, where they account for 10% of all pregnancy losses. Despite the parent-of-origin being important in the etiology of the pregnancy, our knowledge of their causes is limited, especially at the point of conception. Using a dataset of 96,660 biopsies and a validation dataset of 44,324 from human blastocysts embryos generated by intra-cytoplasmic sperm injection (ICSI), we estimate that 1.1% of human conceptions (n=1,063) contain extra or missing chromosome sets in zygotes. We identify a maternal age effect, with a 1.059 per year increased risk in triploidy/haploidy (p=0.0008). In 0.03% of couples, we identified three or more triploid/haploid embryos, suggesting a personal risk effect (p=0.03). Genotype analysis of 55 triploid embryo biopsies and their parents show that one third of maternal triploid conceptions originate in meiosis I and two thirds in meiosis II. Seven of these embryos are inferred to have entirely failed to initiate meiotic recombination genome-wide, suggesting that human oocytes with pervasive meiotic recombination failure that are formed during fetal development are capable of ovulation in adult life. Finally, we identify a new type of genome-wide maternal isodiploidy (two maternal chromosome sets) in 0.05% of embryos (41 of 74,009). Collectively, our findings shed light on the biology of meiosis and the formation of human oocytes with the number of chromosome sets.

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BibTeXRIS

Picchetta, L., Ottolini, C. S., Tao, X., Zhan, Y., Jobanputra, V., Marin Vallejo, C., Mulas, F., Elvezia, E. M., Escriba Perez, M. J., Molinaro, T., Whitehead, C., Gill, P., Mounts, E., Babariya, D., Rienzi, L. F., Ubaldi, F. M., Garcia Velasco, J. A., Pellicer, A., Carmi, S., Hoffmann, E. R., Capalbo, A.. 2025-02-17. Maternal age and genome-wide failure of meiotic recombination are associated with triploid conceptions in humans. https://doi.org/10.1101/2025.02.15.637872

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